Health Conditions Related to Genetic Changes
Jansen-de Vries syndrome
Certain variants (sometimes called mutations) in the PPM1D gene can cause Jansen-de Vries syndrome, a developmental disorder that affects many parts of the body. The variants that cause Jansen-de Vries syndrome occur in particular segments of the PPM1D gene known as exon 5 or exon 6. These variants disrupt the gene's instructions, resulting in an enzyme that does not function as it should. Research suggests that this enzyme is not able to reach the cell's nucleus. Without enough functional enzyme, heterochromatin regulation is disrupted, which likely alters gene expression. Altered gene expression may affect the early development of the brain. Researchers are trying to learn exactly how variants in the PPM1D gene affect the early development of the brain and other body systems to cause the signs and symptoms of Jansen-de Vries syndrome.
More About This Health ConditionOther Disorders
Variants in the PPM1D gene have been found in the tissues of people with various cancers, including breast cancer. These gene variants are known as somatic variants and are acquired during a person's lifetime. The variants are not inherited and are present only in certain cells. Variants in the PPM1D gene that are associated with cancer increase the activity of protein phosphatase 1D, which decreases the activity of tumor protein p53 and allows cancer cells to grow and divide.
Other Names for This Gene
- PP2C-DELTA
- protein phosphatase 1D, magnesium-dependent, delta isoform
- protein phosphatase 2C, delta isoform
- wild-type p53-induced phosphatase 1
- WIP1
Additional Information & Resources
Tests Listed in the Genetic Testing Registry
Scientific Articles on PubMed
Catalog of Genes and Diseases from OMIM
References
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- Lu X, Nannenga B, Donehower LA. PPM1D dephosphorylates Chk1 and p53 and abrogates cell cycle checkpoints. Genes Dev. 2005 May 15;19(10):1162-74. doi: 10.1101/gad.1291305. Epub 2005 May 3. Citation on PubMed
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- Wojcik MH, Srivastava S, Agrawal PB, Balci TB, Callewaert B, Calvo PL, Carli D, Caudle M, Colaiacovo S, Cross L, Demetriou K, Drazba K, Dutra-Clarke M, Edwards M, Genetti CA, Grange DK, Hickey SE, Isidor B, Kury S, Lachman HM, Lavillaureix A, Lyons MJ, Marcelis C, Marco EJ, Martinez-Agosto JA, Nowak C, Pizzol A, Planes M, Prijoles EJ, Riberi E, Rush ET, Russell BE, Sachdev R, Schmalz B, Shears D, Stevenson DA, Wilson K, Jansen S, de Vries BBA, Curry CJ. Jansen-de Vries syndrome: Expansion of the PPM1D clinical and phenotypic spectrum in 34 families. Am J Med Genet A. 2023 Jul;191(7):1900-1910. doi: 10.1002/ajmg.a.63226. Epub 2023 May 14. Citation on PubMed
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